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Case of thyroid hemiagenesis and ectopic lingual thyroid presenting as goitre

  • Y S Yang (a1) and K H Hong (a1)

We report an extremely rare case of thyroid hemiagenesis with ectopic lingual thyroid.


Case report and review of the world literature concerning thyroid hemiagenesis with ectopic lingual thyroid and heredity.


Ectopic thyroid is an uncommon embryological aberration characterised by the presence of thyroid tissue in a site other than its usual, pretracheal location. The lingual thyroid is the most common manifestation of benign ectopic thyroid tissue, but is still a rare clinical entity. Thyroid hemiagenesis is also a very rare abnormality, in which one thyroid lobe fails to develop. We report a case of left thyroid hemiagenesis and goitre in the right lobe in a 26-year-old woman with an ectopic lingual thyroid.


To our knowledge, this is the first report in the world literature of thyroid hemiagenesis with ectopic lingual thyroid.

Corresponding author
Address for correspondence: Dr Yun Su Yang, Department of Otolaryngology-Head and Neck Surgery, Chonbuk National University, Medical School, Chonju, Chonbuk 560-182, South Korea. Fax: 82 63 250 1986 E-mail:
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1 W Shabana , F Delange , M Freson , M Osteaux , J De Schepper . Prevalence of thyroid hemiagenesis: ultrasound screening in normal children. Eur J Pediatr 2000;159:456–8

2 J Piera , J Garriga , R Calabuig , D Bargallo . Thyroidal hemiagenesis. Am J Surg 1986;151:419–21

4 P Mikosch , HJ Gallowitsch , E Kresnik , M Molnar , I Gomez , P Lind . Thyroid hemiagenesis in an endemic goiter area diagnosed by ultrasonography: report of sixteen patients. Thyroid 1999;9:1075–84

5 RJ Wong , MJ Cunningham , HD Curtin . Cervical ectopic thyroid. Am J Otolaryngol 1998;19:397400

6 JC Melnick , PE Stemkowski . Thyroid hemiagenesis (hockey stick sign): a review of the world literature and a report of four cases. J Clin Endocrinol Metab 1981;52:247–51

7 N Karabay , A Comlekci , MS Canda , F Bayraktar , B Degirmenci . Thyroid hemiagenesis with multinodular goiter: a case report and review of the literature. Endocr J 2003;50:409–13

9 SH Baik , JH Choi , HM Lee . Dual ectopic thyroid. Eur Arch Otorhinolaryngol 2002;259:105–7

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The Journal of Laryngology & Otology
  • ISSN: 0022-2151
  • EISSN: 1748-5460
  • URL: /core/journals/journal-of-laryngology-and-otology
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