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Congenital salivary fistula of an accessory parotid gland in Goldenhar syndrome

Published online by Cambridge University Press:  28 October 2011

Z Sun ,
L Sun ,
Z Zhang  and
X Ma
Z Sun
Affiliation:
Department of Oral and Maxillofacial Radiology, School and Hospital of Stomatology, Peking University, Beijing, China
L Sun
Affiliation:
Central Laboratory of Oral Pathology, School and Hospital of Stomatology, Peking University, Beijing, China
Z Zhang
Affiliation:
Department of Oral and Maxillofacial Radiology, School and Hospital of Stomatology, Peking University, Beijing, China
X Ma*
Affiliation:
Department of Oral and Maxillofacial Radiology, School and Hospital of Stomatology, Peking University, Beijing, China
*
Address for correspondence: Dr Xuchen Ma, Department of Oral and Maxillofacial Radiology, School and Hospital of Stomatology, Peking University, 22 Zhongguancun South Street, Haidian District, Beijing 100081, P R China Fax: +86 10 62173402 E-mail: kqxcma@bjmu.edu.cn
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Abstract

Objectives:

We report two cases of congenital salivary fistula of an accessory parotid gland, and we discuss its occurrence in Goldenhar syndrome.

Methods:

Two teenagers complained of a congenital cheek fistula with constant salivary discharge. Computed tomography fistulography and sialography were performed. The diagnosis of Goldenhar syndrome was established based on clinical and imaging findings. Previously reported cases are reviewed and the clinical and radiological features summarised.

Results:

In these two patients, a salivary fistula of an accessory parotid gland was demonstrated on computed tomography fistulography, and did not communicate with Stensen's duct. Deformity of Stensen's duct and hypoplasia of the ipsilateral mandibular ramus were present. Tragal appendices have frequently been reported in such cases.

Conclusion:

A congenital cheek salivary fistula of an accessory parotid gland should be considered indicative of Goldenhar syndrome.

Keywords

ChildGoldenhar SyndromeParotid Gland, AbnormalityFistulaComputed Tomography
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 126 , Issue 1 , January 2012 , pp. 103 - 107
Copyright
Copyright © JLO (1984) Limited 2011

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References

1Mahore, A, Dange, N, Nama, S, Goel, A. Facio-auriculo-vertebro-cephalic spectrum of Goldenhar syndrome. Neurol India 2010;58:141–4CrossRefGoogle ScholarPubMed
2Vinay, C, Reddy, RS, Uloopi, KS, Madhuri, V, Sekhar, RC. Craniofacial features in Goldenhar syndrome. J Indian Soc Pedod Prev Dent 2009;27:121–4CrossRefGoogle ScholarPubMed
3Tiner, BD, Quaroni, AL. Facial asymmetries in hemifacial microsomia, Goldenhar syndrome, and Treacher Collins syndrome. Atlas Oral Maxillofac Surg Clin North Am 1996;4:37–52CrossRefGoogle ScholarPubMed
4Gadodia, A, Seith, A, Sharma, R, Thakar, A. Congenital salivary fistula of accessory parotid gland: imaging findings. J Laryngol Otol 2008;122:E11CrossRefGoogle ScholarPubMed
5Moon, WK, Han, MH, Kim, IO, Sung, MW, Chang, KH, Choo, SW et al. Congenital fistula from ectopic accessory parotid gland: diagnosis with CT sialography and CT fistulography. AJNR Am J Neuroradiol 1995;16:997–9Google ScholarPubMed
6Yamasaki, H, Tashiro, H, Watanabe, T. Congenital parotid gland fistula. Int J Oral Maxillofac Surg 1986;15:492–4CrossRefGoogle ScholarPubMed
7Zhao, K, Wang, LM, Qi, DY. Congenital extraoral fistula from an auxiliary parotid gland. J Oral Maxillofac Surg 1992;50:752–3Google ScholarPubMed
8Hah, JH, Kim, BJ, Sung, MW, Kim, KH. Chemocauterization of congenital fistula from the accessory parotid gland. Clin Exp Otorhinolaryngol 2008;1:113–15CrossRefGoogle ScholarPubMed
9Currarino, G, Votteler, TP. Lesions of the accessory parotid gland in children. Pediatr Radiol 2006;36:1–7CrossRefGoogle ScholarPubMed
10Yoshihara, T, Suzuki, S, Nagao, K. Mucoepidermoid carcinoma arising in the accessory parotid gland. Int J Pediatr Otorhinolaryngol 1999;48:47–52CrossRefGoogle ScholarPubMed
11Lin, DT, Coppit, GL, Burkey, BB, Netterville, JL. Tumors of the accessory lobe of the parotid gland: a 10-year experience. Laryngoscope 2004;114:1652–5CrossRefGoogle Scholar
12Frommer, J. The human accessory parotid gland: its incidence, nature, and significance. Oral Surg Oral Med Oral Pathol Oral Radiol Endod 1977;43:671–6CrossRefGoogle Scholar
13Mukherji, SK, Fatterpekar, G, Castillo, M, Stone, JA, Chung, CJ. Imaging of congenital anomalies of the branchial apparatus. Neuroimaging Clin N Am 2000;10:75–93, viiiGoogle ScholarPubMed
14Miller, TD, Metry, D. Multiple accessory tragi as a clue to the diagnosis of the oculo-auriculo-vertebral (Goldenhar) syndrome. J Am Acad Dermatol 2004;50(suppl 2):S11–13CrossRefGoogle Scholar