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Bronchogenic cysts as a cause of infantile stridor: case report and literature review

Published online by Cambridge University Press:  18 July 2011

J Goswamy ,
S de Kruijf ,
G Humphrey ,
M P Rothera  and
I A Bruce
J Goswamy*
Affiliation:
Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Manchester, UK
S de Kruijf
Affiliation:
Erasmus Medical School, Rotterdam, The Netherlands
G Humphrey
Affiliation:
Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Manchester, UK
M P Rothera
Affiliation:
Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Manchester, UK
I A Bruce
Affiliation:
Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Manchester, UK University of Manchester, UK
*
Address for correspondence: Mr J Goswamy, Department of Otorhinolaryngology – Head and Neck Surgery, Royal Manchester Children's Hospital, Oxford Road, Manchester M13 9WL, UK E-mail: jaygoswamy@doctors.org.uk
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Abstract

Introduction:

Cystic lesions related to the upper airway are an unusual cause of infantile stridor. Such a lesion may exert a mass effect, with subsequent airway compromise.

Case report:

A six-month-old boy was transferred to our unit with a right-sided, level IV neck lump and a three-month history of chronic cough and, latterly, inspiratory stridor. Computed tomography revealed a large, unilocular, cystic, cervicothoracic lesion causing marked compression of the trachea. Airway endoscopy subsequently revealed the larynx to be displaced to the left, with severe external compression of the trachea from just below the subglottic level to immediately above the carina. The mediastinal lesion was excised via an external approach. The histological diagnosis was a bronchogenic cyst.

Conclusion:

Bronchogenic cysts are a rare cause of infantile stridor, and should be considered in the differential diagnosis of cystic cervical and mediastinal masses. Surgical excision is the treatment of choice.

Keywords

Bronchogenic CystInfantStridor
Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 125 , Issue 10 , October 2011 , pp. 1094 - 1097
Copyright
Copyright © JLO (1984) Limited 2011

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Footnotes

Presented at the 139th Semon Club Meeting, 21 May 2010, Guy's Hospital, London, UK

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