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Lymphangioma circumscriptum of the tongue: successful treatment using intralesional bleomycin

Published online by Cambridge University Press:  23 June 2009

P Kataria ,
J C Passey  and
A K Agarwal
P Kataria*
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Maulana Azad Medical College and Associated Hospitals, New Delhi, India
J C Passey
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Maulana Azad Medical College and Associated Hospitals, New Delhi, India
A K Agarwal
Affiliation:
Department of Otorhinolaryngology and Head and Neck Surgery, Maulana Azad Medical College and Associated Hospitals, New Delhi, India
*
Address for correspondence: Dr Pooja Kataria, Department of Otorhinolaryngology and Head And Neck Surgery, Maulana Azad Medical College and Associated Hospitals, Bahadur Shah Zafar Marg, New Delhi 110002, India. Fax: 91 11 23967023 E-mail: drpooja_kataria@yahoo.com
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Abstract

Objective:

We report a case of lymphangioma circumscriptum of the tongue, a very rare site of occurrence, which was successfully managed with intralesional bleomycin therapy.

Method:

We present a case report and review of available literature regarding lymphangioma circumscriptum of the tongue and the role of bleomycin therapy.

Results:

The patient was a 19-year-old man with a long-standing lesion involving the tongue, who presented with spontaneous, episodic bleeding over the previous few months. A diagnosis of lymphangioma circumscriptum was established on biopsy. Intralesional bleomycin injection resulted in successful resolution, and the patient remained asymptomatic over more than one year's follow up.

Conclusion:

Lymphangioma circumscriptum is usually seen in the extremities and genitals. This case had a very rare site of occurrence, the tongue, and was successfully managed with conservative treatment, using intralesional bleomycin alone.

Keywords

LymphangiomaLymphangioma CircumscriptumLymphatic MalformationTongueBleomycin

Information

Type
Clinical Records
Information
The Journal of Laryngology & Otology , Volume 123 , Issue 12 , December 2009 , pp. 1390 - 1392
Copyright
Copyright © JLO (1984) Limited 2009

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